A malignant bilateral sertoli leydig cell tumour in pregnancy is a rare entity. It presents a
challenging situation to the obstetrician and requires a team approach in consultation with the
oncologist. 22 year old female presented to us at 5 months of pregnancy with ?fibroid of uterus.
She was managed till term in ward and elective LSCS was done, when intra operatively she was
found to have bilateral ovarian tumour. On histopathology it was diagnosed to be a rare case of
poorly differentiated malignant sertoli leydig cell tumour which was hormonally inactive. Patient
was then operated for total abdominal hysterectomy with bilateral salpingectomy with
right ovariectomy with omentectomy with lymph node dissection. She was then referred to
Tata hospital for chemotherapy. In present case the management has resulted in a favourable
outcome in the form of a healthy mother