Priapism is a prolonged penile erection not associated with sexual arousal. It is a rare complication of haematological disease. Among Leukaemia, it is most frequently seen in patients with chronic myeloid leukaemia, due to high leucocyte count that these patients achieve. We report a 32 year old male, a known case of chronic myeloid leukaemia in remission phase presenting with priapism. He responded well to aspiration.